Telehealth Delivery of Speech–Language Pathology Services for Children with Cleft Palate and Velopharyngeal Dysfunction: A Systematic Review
Abstract
1. Introduction
2. Materials and Methods
2.1. Protocol and Registration
2.2. Eligibility Criteria (PICOS)
2.3. Information Sources
2.4. Search Strategy
2.5. Selection Process
2.6. Data Collection Process and Data Items
2.7. Risk-of-Bias Assessment
| CASP Criterion | [20] | [21] | [15] | [22] | [23] | [6] |
|---|---|---|---|---|---|---|
| 1. Focused issue | Yes | Yes | Yes | Yes | Yes | Yes |
| 2. Appropriate method | Yes | Yes | Yes | Yes | Yes | Yes |
| 3. Subjects recruited acceptably | Yes | Yes | Yes | Cannot tell | Cannot tell | Yes |
| 4. Measures accurately measured | Yes | Yes | Cannot tell | Yes | Yes | Yes |
| 5. Data collection addressed issue | Yes | Yes | Cannot tell | Yes | Yes | Yes |
| 6. Enough participants | No | Yes | No | Cannot tell | No | Cannot tell |
| 7. Results presented | Yes | Yes | Cannot tell | Yes | Yes | Yes |
| 8. Rigorous data analysis | No | Yes | No | Cannot tell | Yes | Yes |
| 9. Clear statement of findings | Yes | Yes | Yes | Yes | Yes | Yes |
| 10. Applicability to population | Yes | Yes | Yes | Yes | Cannot tell | Yes |
| 11. Value of the research | Yes | Yes | Yes | Yes | Yes | Yes |
| Overall risk of bias | Moderate | Low–Moderate | Moderate | Moderate | Moderate–High | Low–Moderate |
| CASP Criterion | [16] | [24] | [25] |
|---|---|---|---|
| 1. Focused issue | Yes | Yes | Yes |
| 2. Appropriate method | Yes | Yes | Yes |
| 3. Subjects recruited acceptably | Cannot tell | Cannot tell | Cannot tell |
| 4. Measures accurately measured | Cannot tell | Yes | Yes |
| 5. Data collection addressed issue | Yes | Yes | Yes |
| 6. Enough participants | Cannot tell | Cannot tell | Cannot tell |
| 7. Results presented | Yes | Yes | Yes |
| 8. Rigorous data analysis | Cannot tell | Cannot tell | Yes |
| 9. Clear statement of findings | Yes | Yes | Yes |
| 10. Applicability to population | Yes | Yes | Yes |
| 11. Value of the research | Yes | Yes | Yes |
| Overall risk of bias | Moderate | Moderate | Moderate |
| Domain | [26] | Risk Judgment |
|---|---|---|
| Randomization process | Computer-generated sequence; independent allocation | Low risk |
| Deviations from intended interventions | Parent-delivered therapy; no blinding; potential protocol deviations | Some concerns |
| Missing outcome data | Minimal attrition; balanced across groups | Low risk |
| Measurement of the outcome | Outcome assessors likely unblinded | High risk |
| Selection of the reported results | No preregistered protocol; potential selective reporting | Some concerns |
| Overall risk of bias | Combination of minor and measurement-related concerns | Some concerns |
= Low risk,
= Some concerns,
= High risk.2.8. Effect Measures
2.9. Synthesis Methods (SWiM)
2.10. Reporting Bias Assessment
2.11. Certainty Assessment
3. Results
3.1. Study Selection
3.2. Risk of Bias
3.3. Study Characteristics and Extracted Data
| Authors (Year) | Study Design | Sample Size | Setting | Age Range (Years) | N with CP/VPD |
|---|---|---|---|---|---|
| [20] | Pilot telepractice parent training (single-group study) | 3 cleft + 1 control | USA (telepractice) | 1.75–2.25 | 3 |
| [21] | Pre–post intervention | 43 (completed) | Mexico (Hablarte e Integrarte A.C.) | 4–12 (M = 7.04, SD = 2.59) | 43 |
| [25] | Pre–post prospective study | 19 | Thailand (Srinagarind Hospital) | 5–13 | 19 |
| [22] | Observational pre–post study | 16 | Japan (Aichi Gakuin University Dental Hospital) | ~4–12 (M = 6.4) | 16 |
| [26] | Randomized controlled trial | 44 | UK and Ireland | 2.75–7.17 | 44 |
| [6] | Cross-sectional comparative study (Remote vs. In-Person assessment) | 9 | Mexico and USA | 5–14 | 9 |
| [24] | Descriptive cross-sectional study (tele-therapy, cross-border) | 8/10 completed | Baltimore, USA, and Nicaragua | 3–17 | 8 |
| [16] | Service evaluation (virtual MDT clinic) | N/A | N/A | N/A | N/A |
| [13] | Cross-sectional survey | 212 | UK (Cleft Collective) | 0.5–12.4 | 212 |
| [23] | Observational case study (telepractice) | 1 | Hong Kong | 10 | 1 |
| [15] | Service delivery report (virtual MDT; Zoom/MyChart) | N/A | USA | N/A | N/A |
3.4. Synthesis by Outcome Domain
| Authors (Year) | Intervention | Main Results |
|---|---|---|
| [20] | EMT+PE delivered via telepractice (parent coaching) | Increased parent strategy use; gains in talking rate, speech production, and expressive vocabulary. (post-treatment follow-up only). |
| [21] | Group SLP via telepractice (Whole Language Model) | Significant improvement in compensatory articulation severity (p < 0.001). (post-treatment follow-up only). |
| [25] | Hybrid face-to-face and Zoom telepractice | Significant improvements in PCC, resonance, intelligibility, and acceptability; high caregiver satisfaction. (3-month follow-up). |
| [22] | Telepractice therapy during COVID-19 | Outcomes improved or maintained; 100% parental satisfaction. (post-treatment follow-up only). |
| [26] | Parent-led articulation therapy via Video vs. Routine care | Both groups improved; no significant between-group differences (parity with usual care). (3-month RCT follow-up). |
| [6] | Real-time Remote vs. In-Person assessment | High agreement on many parameters; weaker for airflow/nasality-dependent features. (single assessment session). |
| [24] | Tele-SLP with interpreter support (cross-border) | Articulation gains; improved social participation/quality of life. (post-treatment follow-up only). |
| [16] | Virtual MDT clinic (JPRAS) | Preserved care planning/continuity; identified practical constraints. (follow-up period not specified). |
| [13] | Tele-SLP service during COVID-19 | Most parents rated therapy as at least “somewhat effective”; tech/engagement issues noted. (service-period survey). |
| [23] | Telepractice articulation therapy (VPD; Cantonese) | Positive speech production changes with strong parent involvement. (post-treatment follow-up only). |
| [15] | Virtual MDT (Zoom/MyChart) | Enabled flexible coordination; reduced travel needs. (follow-up period not specified). |
| Authors (Year) | Effectiveness | Satisfaction | Accessibility |
|---|---|---|---|
| [20] | Improved speech/language via caregiver-mediated model (post-treatment follow-up only). | Not explicitly reported | Feasible for toddlers at home |
| [21] | Significant articulation improvements (post-treatment follow-up only). | Not reported | High; group telepractice is workable |
| [25] | Improved PCC/resonance/intelligibility (3-month follow-up). | Very high caregiver satisfaction | High; reduced costs/burden |
| [22] | Maintained/improved therapy outcomes (post-treatment follow-up only). | 100% parental satisfaction | High for families with internet/video |
| [26] | Telehealth ≈ routine care on primary outcomes (3-month RCT follow-up). | Positive feedback in feasibility phase | Video platform bridged gaps |
| [6] | Remote ≈ in-person for many perceptual ratings (single assessment session). | Positive parent feedback | Cross-border evaluation feasible |
| [24] | Articulation gains; QOL improvements (post-treatment follow-up only). | High satisfaction (parent-reported) | Interpreter-supported cross-border model |
| [16] | MDT continuity: SLP components preserved (follow-up period not specified). | Not formally measured | Reduced travel; flexible planning |
| [13] | Most rated therapy “somewhat/very effective” (service-period survey). | Generally positive; engagement/tech issues | Access dependent on connectivity |
| [23] | Positive articulation changes in case study (post-treatment follow-up only). | Inferred high (family engagement) | Effective despite constraints |
| [15] | MDT coordination maintained (follow-up period not specified). | Provider-reported positives | Enabled access for remote families |
4. Discussion
4.1. Effectiveness of Telehealth Interventions
4.2. Satisfaction with Telehealth
4.3. Accessibility and Equity
4.4. Strengths and Limitations of This Review
4.5. Implications for Practice and Research
- Professionals should apply telehealth strategically for triage, caregiver coaching, and routine follow-up within multidisciplinary (MDT) pathways; targeted in-person sessions remain essential for complex perceptual or instrumental assessments (e.g., resonance or airflow evaluation) [6].
- (i)
- Adequately powered comparative trials with standardized and blinded outcome assessment;
- (ii)
- Validation of remote measures for resonance and nasality, including acoustic or automated approaches;
- (iii)
- Implementation and dose–response studies to define minimum effective telehealth intensity;
- (iv)
- Cost-effectiveness and digital equity evaluations;
- (v)
- Long-term follow-up examining participation and quality-of-life outcomes and the use of multicentre randomized controlled designs with standardized outcome sets to strengthen external validity and durability of findings.
5. Conclusions
Supplementary Materials
Author Contributions
Funding
Institutional Review Board Statement
Informed Consent Statement
Data Availability Statement
Conflicts of Interest
References
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Al Awaji, N.N.; Alsinan, A.N.; Alamri, R.S.; Bin Ruaydan, N.A.; Alharbi, L.S.; Albesher, L.T.; Alrutaiq, L. Telehealth Delivery of Speech–Language Pathology Services for Children with Cleft Palate and Velopharyngeal Dysfunction: A Systematic Review. Children 2025, 12, 1523. https://doi.org/10.3390/children12111523
Al Awaji NN, Alsinan AN, Alamri RS, Bin Ruaydan NA, Alharbi LS, Albesher LT, Alrutaiq L. Telehealth Delivery of Speech–Language Pathology Services for Children with Cleft Palate and Velopharyngeal Dysfunction: A Systematic Review. Children. 2025; 12(11):1523. https://doi.org/10.3390/children12111523
Chicago/Turabian StyleAl Awaji, Nisreen Naser, Alanoud Nawaf Alsinan, Raja S. Alamri, Nourah A. Bin Ruaydan, Lama S. Alharbi, Lana T. Albesher, and Latifa Alrutaiq. 2025. "Telehealth Delivery of Speech–Language Pathology Services for Children with Cleft Palate and Velopharyngeal Dysfunction: A Systematic Review" Children 12, no. 11: 1523. https://doi.org/10.3390/children12111523
APA StyleAl Awaji, N. N., Alsinan, A. N., Alamri, R. S., Bin Ruaydan, N. A., Alharbi, L. S., Albesher, L. T., & Alrutaiq, L. (2025). Telehealth Delivery of Speech–Language Pathology Services for Children with Cleft Palate and Velopharyngeal Dysfunction: A Systematic Review. Children, 12(11), 1523. https://doi.org/10.3390/children12111523

